Definition: inherited genetic disorder characterized by the impaired break down of branched-chain amino acids (BCAA)

Epidemiology


Etiology

autosomal recessive


Pathophysiology

  • Absent or deficient branched-chain alpha-ketoacid dehydrogenase → impaired degradation of BCAA (valine, leucine, isoleucine) → elevated α-ketoacid formationPasted image 20231117163430.png

Clinical features

  • Symptom onset: early neonatal period
  • Vomiting, lethargy, poor feeding
  • Sweet-smelling urine (maple syrup or burnt sugar odor)
  • Intellectual disability
  • Dystonia
  • Damage to the CNS can be severe (elevated leucine level leads to brain injury)
  • Death may occur without appropriate treatment

Diagnostics

  • Serum
    • Increased levels of alpha-ketoacids (especially leucine alpha-ketoacids)

Treatment

  • Avoid foods containing BCAA
  • Supplementation of thiamine, a cofactor of branched-chain alpha-ketoacid dehydrogenase